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Neurobiology of Disease
|
2025
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Human iPSC-derived glutamatergic neurons with pathogenic KCNQ2 variants display hyperactive bursting phenotypes

Maria Sundberg, Carole Shum, Erika M. Norabuena, Nina R. Makhortova, Cidi Chen, Lucy Yu, Emma V. Wightman, Kristina Kim, Sang Yeon Han, Jennifer Howe, Annapurna Poduri, Elizabeth D. Buttermore, Stephen W. Scherer, Mustafa Sahin
Journal Article
Disease Modeling
Neuronal Cell Cultures
MaxLab Live
MaxTwo
Translational Vision Science & Technology
|
2025
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Sustained Neurotrophic Factor Co-Treatment Enhances Donor and Host Retinal Ganglion Cell Survival in Mice

Jonathan R. Soucy, Julia Oswald, Emil Kriukov, Monichan Phay, John Masland, Christian Pernstich, Petr Baranov
Journal Article
Functional Phenotyping
Retina
MaxLab Live
MaxOne
Brain
|
2025
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A human striatal-midbrain assembloid model of alpha-synuclein propagation

Hoang-Dai Tran, Min-Kyoung Shin, Xin Yi Yeo, Sangyong Jung, Muhammad Junaid, Su Bin Lim, Jungmo Kim, Hyun Goo Woo, Charlotte R Denman, Run-Run Han
Journal Article
Disease Modeling
Organoids
MaxLab Live
MaxOne
bioRxiv
|
2025
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Incubator-Free Organoid Culture in a Sealed Recirculatory System

Yohei Rosen, Kivilcim Doganyigit, Santhosh Arul, Eliot Wachtel, Drew Ehrlich, Vaishnavi Venuturimilli, Matilda Mouzaya, Sophia Oriaku, Bi Ndiforchu, Gregory Kaurala, Sebastian Hernandez, Maryam Moarefian, Hunter Schweiger, Ariana Cisneros, Mojtaba Zeraatkar, Jinghui Geng, Mohammed A. Mostajo-Radji, Ethan Winkler, David Haussler, Mircea Teodorescu
Preprint
Functional Phenotyping
Method Development
Organoids
MaxOne
bioRxiv
|
2025
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Interspecies Organoids Reveal Human-Specific Molecular Features of Dopaminergic Neuron Development and Vulnerability

Sara Nolbrant, Jenelle L. Wallace, Jingwen W. Ding, Tianjia Zhu, Jess L. Sevetson, Janko Kajtez, Isabella A. Baldacci, Emily K. Corrigan, Kaylynn Hoglin, Reed McMullen, Megan S. Ostrowski, Matthew T. Schmitz, Arnar Breevoort, Dani Swope, Fengxia Wu, Bryan J. Pavlovic, Sofie R. Salama, Agnete Kirkeby, Hao Huang, Nathan K. Schaefer, Alex A. Pollen
Preprint
Functional Phenotyping
Organoids
MaxLab Live
MaxOne
Frontiers in Neural Circuits
|
2025
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Deviance detection and regularity sensitivity in dissociated neuronal cultures

Zhuo Zhang, Amit Yaron, Dai Akita, Tomoyo Isoguchi Shiramatsu, Zenas C. Chao, Hirokazu Takahashi
Journal Article
Functional Phenotyping
Pharmacology & Toxicology
Neuronal Cell Cultures
MaxOne
Communications Biology
|
2025
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Human neural organoid microphysiological systems show the building blocks necessary for basic learning and memory

Dowlette-Mary Alam El Din, Leah Moenkemoeller, Alon Loeffler, Forough Habibollahi, Jack Schenkman, Amitav Mitra, Tjitse van der Molen, Lixuan Ding, Jason Laird, Maren Schenke, Erik C. Johnson, Brett J. Kagan, Thomas Hartung, Lena Smirnova
Journal Article
Functional Phenotyping
MaxLab Live
MaxTwo
Research Square
|
2025
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Epigenetic Reactivation of CDKL5 Rescues CDKL5 Deficiency Disorder

Kyle Fink, Julian Halmai, David Cameron, Casiana Gonzalez, Mandeep Singh, Anber Ansari, Viktoria Haghani, Emma Monsen, Alyssa Paynton-Cheney, Jennifer Waldo, Timothy Fenton, Roy Ben-Shalom, Jill Silverman
Preprint
Disease Modeling
Pharmacology & Toxicology
Organoids
MaxLab Live
MaxOne
bioRxiv
|
2025
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Online supervised learning of temporal patterns in biological neural networks under feedback control

Yuki Sono, Hideaki Yamamoto, Yusei Nishi, Takuma Sumi, Yuya Sato, Ayumi Hirano-Iwata, Yuichi Katori, Shigeo Sato
Preprint
Microphysiological Systems
Neuronal Cell Cultures
MaxOne
Cyborg and Bionic Systems (Washington, D.C.)
|
2025
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Dynamic Network Plasticity and Sample Efficiency in Biological Neural Cultures: A Comparative Study with Deep Reinforcement Learning

Moein Khajehnejad, Forough Habibollahi, Alon Loeffler, Aswin Paul, Adeel Razi, Brett J. Kagan
Journal Article
Neuronal Cell Cultures
MaxOne
Advanced Therapeutics
|
2025
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Topology and Mechanism of Broadband and Fast Multi‐Characteristic Opsin for Neuromodulation

Samarendra Mohanty, Pratyajit Mohapatra, Amir Singh, William Marks, Subrata Batabyal, Michael Carlson, Najam Sharif, Sanghoon Kim
Journal Article
Functional Phenotyping
Retina
MaxLab Live
MaxOne
Biosensors and Bioelectronics
|
2025
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An in vitro platform for characterizing axonal electrophysiology of individual human iPSC-derived nociceptors

Blandine F. Clément, Lorenzo Petrella, Lea Wallimann, Jens Duru, Christina M. Tringides, János Vörös, Tobias Ruff
Journal Article
Functional Phenotyping
Method Development
Microphysiological Systems
Pharmacology & Toxicology
Organoids
MaxOne
bioRxiv
|
2025
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HydroMEA: A 3D Hydrogel Based Microfluidic Device to Study Electrophysiology for Myelinated Nerve-on-Chip

Blandine F. Clément, Cédric Pfister, Timothy Kurer, Céline Labouesse, Dhanajay V. Deshmukh, Julian Hengsteler, Julia Lehmann, Lorenza G. Paganella, Tobias Ruff, Vilius Dranseika, Sean Weaver, Lukas Sommer, Mark W. Tibbitt, János Vörös, Christina M. Tringides
Preprint
Functional Phenotyping
Method Development
Microphysiological Systems
Organoids
MaxOne
bioRxiv
|
2025
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Triple-Negative Breast Cancer Cells Activate Sensory Neurons via TRPV1 to Drive Nerve Outgrowth and Tumor Progression

Hanan Bloomer, Savannah R. Parker, Audrey L. Pierce, Wesley Clawson, Mallory M. Caron, Thomas Gerton, Ankit Pandey, Thanh T. Le, Tolulope Adewumi, Charlotte Kuperwasser, Michael Levin, Madeleine J. Oudin
Preprint
Disease Modeling
Functional Phenotyping
Neuronal Cell Cultures
MaxOne
bioRxiv
|
2025
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KCNQ2 Loss-of-Function variants disrupt neuronal maturation via early hyperexcitability followed by maladaptive network remodeling

N. Dirkx, M. Kaji, E. De Vriendt, G. Carleo, F. Miceli, B. Asselbergh, P. Verstraelen, N. Zonnekein, L. Carotenuto, L. T. Dang, V. Sommers, E. Vlaemynck, L. Lagae, B. Ceulemans, P. De Jonghe, W. H. De Vos, M. Taglialatela, S. Weckhuysen
Preprint
Disease Modeling
Pharmacology & Toxicology
Neuronal Cell Cultures
MaxLab Live
MaxTwo
British Journal of Pharmacology
|
2025
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The fast-dissociating D2 antagonist antipsychotic JNJ-37822681 is a neuronal Kv7 channel opener: Potential repurposing for epilepsy treatment

Lidia Carotenuto, Oliver Keminer, Giusy Carleo, Andrea Zaliani, Antonio Leo, Rita Citraro, Giovambattista De Sarro, Nina Dirkx, Marcus Kaji, Sarah Weckhuysen, Jeanette Reinshagen, Vincenzo Barrese, Natascia Guida, Carmine Ostacolo, Francesco Miceli, Philip Gribbon, Maurizio Taglialatela
Journal Article
Pharmacology & Toxicology
Neuronal Cell Cultures
MaxLab Live
MaxTwo
bioRxiv
|
2025
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Distinct Synaptic Mechanisms Drive NRXN1 Variant-Mediated Pathogenesis in iPSC-Derived Neuronal Models of Autism and Schizophrenia

Jay English, Danny McSweeney, Jinghui Geng, Ethan Howell, Fumiko Ribbe, Matthew Hinderhofer, Lydia Proskauer, Rebecca Sebastian, Le Wang, Tal Sharf, Zhiping P. Pang, ChangHui Pak
Preprint
Disease Modeling
Functional Phenotyping
Neuronal Cell Cultures
MaxLab Live
MaxOne
Nature Neuroscience
|
2025
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Synchronization of visual perception within the human fovea

Annalisa Bucci, Marc Büttner, Niklas Domdei, Federica B. Rosselli, Matej Znidaric, Julian Bartram, Tobias Gänswein, Roland Diggelmann, Martina De Gennaro, Cameron S. Cowan, Wolf Harmening, Andreas Hierlemann, Botond Roska, Felix Franke
Journal Article
Functional Phenotyping
Retina
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bioRxiv
|
2025
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ALG13 loss-of-function alters glycosylation, impairs neuronal maturation, and drives network hypoactivity in a cortical organoid model of CDG

Rameen Shah, Rohit Budhraja, Silvia Radenkovic, Graeme Preston, Alexia Tyler King, Sahar Sabry, Charlotte Bleukx, Ibrahim Shammas, Lyndsay Young, Jisha Chandran, Seul Kee Byeon, Ronald Hrstka, Doughlas Y. Smith, Nathan P. Staff, Richard Drake, Steven A. Sloan, Akhilesh Pandey, Eva Morava, Tamas Kozicz
Preprint
Disease Modeling
Organoids
MaxLab Live
MaxTwo
Science
|
2025
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Human neuron subtype programming via single-cell transcriptome-coupled patterning screens

Hsiu-Chuan Lin, Jasper Janssens, Benedikt Eisinger, Philipp Hornauer, Ann-Sophie Kroell, Malgorzata Santel, Maria Pascual-Garcia, Ryoko Okamoto, Kyriaki Karava, Zhisong He, Marthe Priouret, Manuel Schröter, J. Gray Camp, Barbara Treutlein
Journal Article
Functional Phenotyping
Neuronal Cell Cultures
MaxLab Live
MaxTwo
eLife
|
2025
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Homophilic wiring principles underpin neuronal network topology in vitro

Danyal Akarca, Alexander WE Dunn, Philipp J Hornauer, Silvia Ronchi, Michele Fiscella, Congwei Wang, Marco Terrigno, Ravi Jagasia, Petra E Vértes, Susanna B Mierau, Ole Paulsen, Stephen J Eglen, Andreas Hierlemann, Duncan E Astle, Manuel Schröter
Journal Article
Functional Phenotyping
Neuronal Cell Cultures
Organoids
MaxLab Live
MaxOne
MaxTwo
Frontiers in Neuroscience
|
2025
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Sensory-spinal neuron co-culture platform enables analysis of sensory-driven spinal activation

Yuki Miyahara, Kenta Shimba, Kiyoshi Kotani, Yasuhiko Jimbo
Journal Article
Microphysiological Systems
Neuronal Cell Cultures
MaxOne
Internet of Things
|
2025
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A feedback-driven brain organoid platform enables automated maintenance and high-resolution neural activity monitoring

Kateryna Voitiuk, Spencer T. Seiler, Mirella Pessoa de Melo, Jinghui Geng, Tjitse van der Molen, Sebastian Hernandez, Hunter E. Schweiger, Jess L. Sevetson, David F. Parks, Ash Robbins, Sebastian Torres-Montoya, Drew Ehrlich, Matthew A. T. Elliott, Tal Sharf, David Haussler, Mohammed A. Mostajo-Radji, Sofie R. Salama, Mircea Teodorescu
Journal Article
Functional Phenotyping
Method Development
Organoids
MaxLab Live
MaxOne
bioRxiv
|
2025
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Stimulation modulates cell assemblies linked with gene networks in the human temporal cortex ex vivo

H. Moore, M. Dehnad, A. Freelin, B. Granger, S. Subramanian, A. Kulkarni, S. Berto, B. C. Lega, G. Konopka
Preprint
Functional Phenotyping
Brain Slices
MaxLab Live
MaxOne
Journal of Visualized Experiments (JoVE)
|
2025
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High-density Multielectrode Array Recordings of Retinal Waves Using An Electrophysiology Platform

Rishikesh Kumar Gupta, Natalie Clark, Kaylee Yeager, Alexander Fisch, Alexandre Tiriac
Journal Article
Functional Phenotyping
Method Development
Retina
MaxOne
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